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MYOM1 deficiency leads to dilated cardiomyopathy by disrupting the homeostasis of sarcoplasmic reticulum - PubMed

5 days ago
  • #Dilated cardiomyopathy
  • #Sarcoplasmic reticulum
  • #MYOM1
  • MYOM1 deficiency is linked to dilated cardiomyopathy (DCM) and heart failure.
  • Loss-of-function MYOM1 variants disrupt sarcomere integrity and sarcoplasmic reticulum calcium homeostasis.
  • Functional studies show MYOM1 deficiency leads to sarcomeric disorganization and mitochondrial abnormalities.
  • Calcium imaging reveals impaired calcium conduction and blunted intracellular calcium transients.
  • MYOM1 is identified as a potential target for DCM risk stratification and therapy.