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Cofilin hyperphosphorylation triggers TDP-43 pathology in sporadic amyotrophic lateral sclerosis - PubMed

3 days ago
  • #TDP-43
  • #ALS
  • #neurodegeneration
  • Cofilin hyperphosphorylation is linked to TDP-43 pathology in sporadic ALS (SALS).
  • TDP-43 pathology includes cytoplasmic mislocalization, inclusion formation, hyperphosphorylation, and fragmentation.
  • Cofilin regulates actin dynamics; its hyperphosphorylation leads to increased F-actin and disrupted actin equilibrium.
  • Hyperphosphorylated cofilin and altered actin dynamics were observed in SALS patients and TDP-43 disease models.
  • Pharmacological stabilization of F-actin induced TDP-43 pathology and stress granule recruitment.
  • Increased LIMK1 phosphorylation and tropomyosin isoforms 4.1/4.2 were detected in SALS patients.
  • Preventing cofilin phosphorylation (e.g., via S3A peptide) may be a therapeutic strategy for ALS and other neurodegenerative diseases.